ASN's Mission

To create a world without kidney diseases, the ASN Alliance for Kidney Health elevates care by educating and informing, driving breakthroughs and innovation, and advocating for policies that create transformative changes in kidney medicine throughout the world.

learn more

Contact ASN

1401 H St, NW, Ste 900, Washington, DC 20005

email@asn-online.org

202-640-4660

The Latest on X

Kidney Week

Abstract: SA-PO1005

Successful Kidney Transplantation in a Patient with Genetic Hypertension Due to a Pathogenic KLHL3 Mutation: A Case Report

Session Information

Category: Transplantation

  • 2102 Transplantation: Clinical

Authors

  • Najar, Hatem, Thomas Jefferson University Hospital, Philadelphia, Pennsylvania, United States
  • Gianni, Tito, Thomas Jefferson University Hospital, Philadelphia, Pennsylvania, United States
  • Goli, Kiran M., Thomas Jefferson University Hospital, Philadelphia, Pennsylvania, United States
  • Hailemariam, Fitsum T., Thomas Jefferson University Hospital, Philadelphia, Pennsylvania, United States
  • Martinez Cantarin, Maria P., Thomas Jefferson University Hospital, Philadelphia, Pennsylvania, United States
  • Gupta, Maitreyee M., Thomas Jefferson University Hospital, Philadelphia, Pennsylvania, United States
Introduction

We report a case of a successful paired exchange kidney transplant in a patient with Gordon syndrome due to a pathogenic KLHL3 mutation, who developed end-stage kidney disease (ESKD), highlighting the transplant outcomes and long-term renal function.

Case Description

A 24-year-old Caucasian male with early-onset hypertension since age 16, hyperkalemia, and non-adherence to thiazide diuretics was admitted with abdominal pain and vomiting. His family history included early-onset hypertension in his brother, father, and paternal grandmother. His BP was 250/160 mmHg. Laboratory results showed a creatinine of 9.9 mg/dL, potassium of 3.0 mmol/L, sodium of 136 mmol/L, chloride of 91 mmol/L, CO2 of 18 mmol/L, hemoglobin of 10 g/dL, and platelet count of 87,000/µL. Renal ultrasound indicated increased echogenicity of both kidneys, and a glomerulonephritis workup was negative.
Despite aggressive antihypertensive therapy, progressive azotemia required hemodialysis. A kidney biopsy showed severe vascular changes consistent with hypertensive nephrosclerosis, including marked arteriolar and arterial intimal thickening, moderate interstitial fibrosis, and 30-35% tubular atrophy. Genetic testing confirmed a heterozygous pathogenic variant in KLHL3, diagnosing Gordon syndrome.
In September 2024, the patient underwent a successful living-unrelated kidney transplant via a paired exchange program. Early post-transplant complications included acute allograft dysfunction due to volume depletion and hydronephrosis, which improved with timely intervention, stabilizing creatinine at 1.1-1.2 mg/dL. The patient also developed severe post-transplant anemia secondary to parvovirus B19-infection, successfully treated with IVIG, ESA, and blood transfusions. At follow-up, the patient showed excellent allograft function and well-controlled BP on a simplified antihypertensive regimen.

Discussion

This case highlights an atypical presentation of Gordon syndrome due to a pathogenic KLHL3 variant, leading to ESKD and requiring kidney transplantation. The impact of KLHL3 mutations on transplant outcomes remains undefined. Our patient underwent kidney transplantation, resulting in excellent long-term renal function and BP control, demonstrating favorable transplant outcomes for patients with genetic hypertension.

Digital Object Identifier (DOI)